Locus control region explained

A locus control region (LCR) is a long-range cis-regulatory element that enhances expression of linked genes at distal chromatin sites. It functions in a copy number-dependent manner and is tissue-specific, as seen in the selective expression of β-globin genes in erythroid cells.[1] Expression levels of genes can be modified by the LCR and gene-proximal elements, such as promoters, enhancers, and silencers. The LCR functions by recruiting chromatin-modifying, coactivator, and transcription complexes.[2] Its sequence is conserved in many vertebrates, and conservation of specific sites may suggest importance in function.[2] It has been compared to a super-enhancer as both perform long-range cis regulation via recruitment of the transcription complex.[3]

History

The β-globin LCR was identified over 20 years ago in studies of transgenic mice. These studies determined that the LCR was required for normal regulation of beta-globin gene expression.[4] Evidence of the presence of this additional regulatory element came from a group of patients that lacked a 20 kb region upstream of the β-globin cluster that was vital for expression of any of the β-globin genes. Even though all of the genes themselves and the other regulatory elements were intact, without this domain, none of the genes in the β-globin cluster were expressed.[5]

Examples

See also: Human β-globin locus.

Although the name implies that the LCR is limited to a single region, this implication only applies to the β-globin LCR (HBB-LCR). Other studies have found that a single LCR can be distributed in multiple areas around and inside the genes it controls. The β-globin LCR in mice and humans is found 6–22 kb upstream of the first globin gene (epsilon). It controls the following genes:[1] [2]

There is an opsin LCR (OPSIN-LCR) controlling the expression of OPN1LW and the first copies of OPN1MW on the human X chromosome, upstream of these genes.[6] A dysfunctional LCR can cause loss of expression of both opsins, leading to blue cone monochromacy.[7] This LCR is also conserved in teleost fishes including zebrafish.[8]

As of 2002, there are 21 LCR areas known in human.[1] As of 2019, 11 human LCRs are recorded in the NCBI database.[9]

Proposed models of LCR function

Although studies have been conducted to attempt to identify a model of how the LCR functions, evidence for the following models is not strongly supported or precluded.[1]

Looping model

Transcription factors bind to hypersensitive site cores and cause the LCR to form a loop that can interact with the promoter of the gene it regulates.[1]

Tracking model

Transcription factors bind to the LCR to form a complex. The complex moves along the DNA helix until it can bind to the promoter of the gene it regulates. Once bound, the transcriptional apparatus increases gene expression.[1]

Facilitated tracking model

This hypothesis combines the looping and tracking models, suggesting that the transcription factors bind to the LCR to form a loop, which then seeks and binds to the promoter of the gene it regulates.[1]

Linking model

Transcription factors bind to DNA from the LCR to the promoter in an orderly fashion using non-DNA-binding proteins and chromatin modifiers. This changes chromatin conformation to expose the transcriptional domain.[1]

Diseases related to the LCR

Studies in transgenic mice have shown that deletion of the β-globin LCR causes the region of chromosome to condense into a heterochromatic state.[1] [2] This leads to decreased expression of β-globin genes, which can cause β-thalassemia in humans and mice.

Notes and References

  1. Li Q, Peterson KR, Fang X, Stamatoyannopoulos G . Locus control regions . Blood . 100 . 9 . 3077–86 . November 2002 . 12384402 . 2811695 . 10.1182/blood-2002-04-1104 . George Stamatoyannopoulos .
  2. Levings PP, Bungert J . The human beta-globin locus control region . European Journal of Biochemistry . 269 . 6 . 1589–99 . March 2002 . 11895428 . 10.1046/j.1432-1327.2002.02797.x . free .
  3. Gurumurthy A, Shen Y, Gunn EM, Bungert J . Phase Separation and Transcription Regulation: Are Super-Enhancers and Locus Control Regions Primary Sites of Transcription Complex Assembly? . BioEssays . 41 . 1 . e1800164 . January 2019 . 30500078 . 6484441 . 10.1002/bies.201800164 . free .
  4. Gerstein MB, Bruce C, Rozowsky JS, Zheng D, Du J, Korbel JO, Emanuelsson O, Zhang ZD, Weissman S, Snyder M . 6 . What is a gene, post-ENCODE? History and updated definition . Genome Research . 17 . 6 . 669–81 . June 2007 . 17567988 . 10.1101/gr.6339607 . free .
  5. Book: Nussbaum . Robert . McInnes . Roderick . Willard . Huntington . vanc . Thompson &Thompson Genetics in Medicine . 2016 . Elsevier . Philadelphia . 200 . Eighth .
  6. Deeb SS . Genetics of variation in human color vision and the retinal cone mosaic . Current Opinion in Genetics & Development . 16 . 3 . 301–7 . June 2006 . 16647849 . 10.1016/j.gde.2006.04.002 .
  7. Carroll J, Rossi EA, Porter J, Neitz J, Roorda A, Williams DR, Neitz M . Deletion of the X-linked opsin gene array locus control region (LCR) results in disruption of the cone mosaic . Vision Research . 50 . 19 . 1989–99 . September 2010 . 20638402 . 3005209 . 10.1016/j.visres.2010.07.009 . free .
  8. Tam KJ, Watson CT, Massah S, Kolybaba AM, Breden F, Prefontaine GG, Beischlag TV . Regulatory function of conserved sequences upstream of the long-wave sensitive opsin genes in teleost fishes . Vision Research . 51 . 21–22 . 2295–303 . November 2011 . 21971525 . 10.1016/j.visres.2011.09.010 . free .
  9. Web site: Search: "locus control region"[title] AND "Homo sapiens"[porgn] AND alive[prop] ]. NCBI Gene . 20 August 2019.